Phosphorylase kinase of the liver: deficiency in a girl with increased hepatic glycogen.
نویسندگان
چکیده
Studies of a child with glycogenosis revealed an increased concentration of glycogen and low phosphorylase activity in her liver. Using mixtures of homogenates of the patient's liver and of normal liver, we found the low phosphorylase activity to be caused by a deficiency of phosphorylase kinase and not of hepatic phosphorylase. The fact that phosphorylase activity was restored to normal values by the addition of phosphorylase b kinase from rabbit muscle substantiates this conclusion.
منابع مشابه
Hepatic phosphorylase deficiency. Its differentiation from other hepatic glycogenoses.
Fernandes, J., Koster, J. F., Grose, W. F. A., and Sorgedrager, N. (1974). Archives of Disease in Childhood, 49, 186. Hepatic phosphorylase deficiency: its differentiation from other hepatic glycogenoses. Two brothers with glycogen storage disease of the liver are reported. The clinical symptoms were hepatomegaly and a slight muscle hypotonia; hypoglycaemic symptoms seldom occurred. There was d...
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ورودعنوان ژورنال:
- Science
دوره 153 3743 شماره
صفحات -
تاریخ انتشار 1966